A Pediatric Radiology Textbook and Pediatric Radiology Digital Library
Adrenoleukodystrophy
Etiology: Peroxisomal disorder with impaired beta oxidation of very long chain fatty acids with accumulation and inflammatory demyelination in white matter and adrenal failure
Imaging: — 3 zones of myelin loss – necrotic core and enhancing active inflammation and demyelination and advancing demyelination without inflammation — Usually symmetrical confluent posterior involvement — Frontal pattern rare in less than 10% — Posterior to anterior gradient — Centrifugal — Enhancement — Schaumberg zones
Imaging MRI: Splenium also involved early on — T1WI: Hypointensity in white matter areas particularly parieto-occipital regions — T1WI post contrast: Enhancement of leading inflammatory edge of demyelination may correlate with worsening clinical status — T2WI: Hyperintensity in white matter areas particularly parieto-occipital regions
DDX:
Complications:
Treatment:
Clinical: — Classic X-linked adrenoleukodystrophy (X-ALD) – severe and males and usually 5-12 years old — Several other variants – adolescent and adult forms as well as adrenomyeloneuropathy